Association between genotype and pulmonary phenotype in cystic fibrosis patients with severe mutations

J Cyst Fibros. 2011 May;10(3):187-92. doi: 10.1016/j.jcf.2011.01.005. Epub 2011 Feb 26.

Abstract

Background: Despite numerous studies a clear relationship between genotype and pulmonary phenotype has not been established within the group pancreatic insufficient cystic fibrosis (CF) patients. We studied the relationship between class I and class II mutations and pulmonary function in Swedish patients with known CFTR functional classification.

Methods: 170 CF patients with two class II mutations, 18 with two class I mutations and 78 with a combination of class I and II mutations were included in the study. Spirometry was performed when patients were in an optimal clinical condition.

Results: Patients with two class I mutations had lower lung function (FEV(1) and FVC) compared to the group with either a combination of class I and II mutations or two class II mutations.

Conclusion: CF patients carrying two class I mutations risk developing more severe lung disease compared to patients with at least one class II mutation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Cross-Sectional Studies
  • Cystic Fibrosis / complications
  • Cystic Fibrosis / genetics*
  • Cystic Fibrosis / physiopathology
  • Cystic Fibrosis Transmembrane Conductance Regulator / genetics*
  • Exocrine Pancreatic Insufficiency / etiology*
  • Female
  • Forced Expiratory Volume
  • Genetic Predisposition to Disease
  • Genotype*
  • Humans
  • Lung / physiopathology*
  • Male
  • Mutation*
  • Phenotype*
  • Severity of Illness Index
  • Vital Capacity
  • Young Adult

Substances

  • Cystic Fibrosis Transmembrane Conductance Regulator